{
  "abstract": "Hereditary hemorrhagic telangiectasia (HHT) is a rare autosomal dominant vascular disorder that may involve the oral mucosa, providing important diagnostic clues for dental practitioners. This report describes a 54-year-old female presenting with recurrent bleeding from multiple red-purple telangiectatic papules on the dorsal surface of the tongue. Her history included recurrent epistaxis, severe iron deficiency anemia, pulmonary involvement, and a positive family history. The lesions blanched on diascopy. Symptomatic management using electrocautery excision under local anesthesia with prophylactic administration of oral amoxicillin (2 g) was performed. Histopathological examination demonstrated thin-walled vascular spaces containing erythrocytes beneath the epithelium, confirming the diagnosis of HHT. Although postoperative healing was uneventful with immediate bleeding control, recurrence occurred after 1 year, necessitating repeat surgery. This case highlights the progressive and recurrent nature of oral HHT lesions, the importance of early detection, and the need for careful dental management, including antibiotic prophylaxis before invasive procedures associated with a risk of bacteremia in patients with pulmonary involvement.",
  "abstract_shown": true,
  "affiliations": [
    "Department of Oral and Maxillofacial Pathology School of Dentistry, Shahid Beheshti University of Medical Sciences Tehran Iran.",
    "Department of Periodontology School of Dentistry, Shahid Beheshti University of Medical Sciences Tehran Iran.",
    "Department of Oral and Maxillofacial Surgery School of Dentistry, Shahid Beheshti University of Medical Sciences Tehran Iran.",
    "Health Research Center, Chamran Hospital Tehran Iran."
  ],
  "article_type": null,
  "arxiv": null,
  "author_total": 6,
  "authors": [
    {
      "affs": [
        0
      ],
      "name": "Saede Atarbashi-Moghadam",
      "orcid": "0000-0002-1731-2786"
    },
    {
      "affs": [
        0
      ],
      "name": "Ali Lotfi",
      "orcid": "0000-0003-0774-841X"
    },
    {
      "affs": [
        1
      ],
      "name": "Fazele Atarbashi-Moghadam",
      "orcid": "0000-0002-3499-2250"
    },
    {
      "affs": [
        2
      ],
      "name": "Mostafa Alam",
      "orcid": "0000-0003-3827-9708"
    },
    {
      "affs": [
        2
      ],
      "name": "Milad Baseri",
      "orcid": "0000-0001-8531-8699"
    },
    {
      "affs": [
        3
      ],
      "name": "Mohammadreza Kashefi Baher",
      "orcid": "0009-0009-7740-025X"
    }
  ],
  "bibtex": "https://research.draconitic.com/paper/8e1ckq3exm9kx.bib",
  "cited_by": 0,
  "doi": "10.1002/ccr3.73883",
  "fulltext_url": "https://europepmc.org/articles/PMC13741848",
  "id": "8e1ckq3exm9kx",
  "issns": [
    "2050-0904"
  ],
  "landing_url": "https://europepmc.org/article/MED/42997498",
  "language": "eng",
  "licence": "CC-BY",
  "licence_label": "CC BY",
  "licence_source": "article",
  "licence_url": "https://creativecommons.org/licenses/by/4.0/",
  "metadata_licence": null,
  "native_subjects": [
    [
      "openalex",
      "2716|Vascular Anomalies and Treatments"
    ]
  ],
  "openalex": "W7225424080",
  "pdf_url": "https://europepmc.org/articles/PMC13741848?pdf=render",
  "pmcid": "PMC13741848",
  "pmid": "42997498",
  "published": "2026-11-06",
  "publisher": null,
  "ris": "https://research.draconitic.com/paper/8e1ckq3exm9kx.ris",
  "sources": [
    {
      "first_seen": "2026-11-09T15:20:34Z",
      "native_id": "MED:42997498",
      "source": "europepmc",
      "url": "https://europepmc.org/article/MED/42997498"
    }
  ],
  "subjects": [
    {
      "field": "medicine",
      "origin": "openalex:2716|Vascular Anomalies and Treatments",
      "subfield": "human-genetics"
    }
  ],
  "title": "Hereditary Hemorrhagic Telangiectasia of the Tongue: A Rare Case Report.",
  "title_text": "Hereditary Hemorrhagic Telangiectasia of the Tongue: A Rare Case Report.",
  "type": "peer-reviewed",
  "updated_at": "2026-11-10T03:20:49Z",
  "url": "https://research.draconitic.com/paper/8e1ckq3exm9kx",
  "venue": "Clinical case reports",
  "versions": []
}