Compression of the Diseased Segment and Regeneration through Healthy Bone for Salvage of Infected Recurrent Congenital Pseudarthrosis of the Tibia in an Adult: A Case Report
- 1Department of Orthopaedics, Dr. Vasantrao Pawar Medical College Hospital and Research Center, Nashik, Maharashtra, India.
- 2Department of Orthopaedics, Kelkar Hospital, Nashik, Maharashtra, India.
Abstract
Introduction Congenital pseudarthrosis of the tibia (CPT) is a rare dysplastic disorder characterized by persistent non-union and recurrent fracture. Management becomes particularly challenging in multiply operated adults with limb-length discrepancy (LLD), deformity, and compromised local biology. Deep infection involving a previously reconstructed CPT segment further limits conventional fixation options. Case Report An 18-year-old male with recurrent CPT and multiple previous surgical procedures presented with an unstable tibial pseudarthrosis, 5-cm LLD, and ankle valgus. Initial Ilizarov compression failed to achieve union. Subsequent excision of the pseudarthrosis and tricortical iliac crest grafting achieved initial union but was complicated by graft-site fracture and deep Staphylococcus aureus infection. Following radical debridement, a multilevel Ilizarov construct was used to achieve acute compression at the infected pseudarthrosis and proximal tibial distraction osteogenesis in healthy bone. Union, infection eradication, and limb-length restoration were achieved and maintained at 24-month follow-up. Conclusion Simultaneous compression of an infected CPT site and distraction osteogenesis through healthy bone may provide a limb-salvage strategy in complex adult CPT when internal fixation is unsuitable.
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BibTeX
@article{dussa2026compression,
title = {{Compression of the Diseased Segment and Regeneration through Healthy Bone for Salvage of Infected Recurrent Congenital Pseudarthrosis of the Tibia in an Adult: A Case Report}},
author = {Abhishek Dussa and Ketankumar Gandhi and Swapnil Jagdale and Sagar Kelkar},
journal = {Journal of Orthopaedic Case Reports},
year = {2026},
month = nov,
doi = {10.13107/jocr.2026.v16.i11.8386},
url = {https://doi.org/10.13107/jocr.2026.v16.i11.8386},
note = {CC BY-NC},
}
RIS
TY - JOUR
TI - Compression of the Diseased Segment and Regeneration through Healthy Bone for Salvage of Infected Recurrent Congenital Pseudarthrosis of the Tibia in an Adult: A Case Report
AU - Abhishek Dussa
AU - Ketankumar Gandhi
AU - Swapnil Jagdale
AU - Sagar Kelkar
PY - 2026
DA - 2026/11/01
JO - Journal of Orthopaedic Case Reports
DO - 10.13107/jocr.2026.v16.i11.8386
UR - https://doi.org/10.13107/jocr.2026.v16.i11.8386
AB - Introduction Congenital pseudarthrosis of the tibia (CPT) is a rare dysplastic disorder characterized by persistent non-union and recurrent fracture. Management becomes particularly challenging in multiply operated adults with limb-length discrepancy (LLD), deformity, and compromised local biology. Deep infection involving a previously reconstructed CPT segment further limits conventional fixation options. Case Report An 18-year-old male with recurrent CPT and multiple previous surgical procedures presented with an unstable tibial pseudarthrosis, 5-cm LLD, and ankle valgus. Initial Ilizarov compression failed to achieve union. Subsequent excision of the pseudarthrosis and tricortical iliac crest grafting achieved initial union but was complicated by graft-site fracture and deep Staphylococcus aureus infection. Following radical debridement, a multilevel Ilizarov construct was used to achieve acute compression at the infected pseudarthrosis and proximal tibial distraction osteogenesis in healthy bone. Union, infection eradication, and limb-length restoration were achieved and maintained at 24-month follow-up. Conclusion Simultaneous compression of an infected CPT site and distraction osteogenesis through healthy bone may provide a limb-salvage strategy in complex adult CPT when internal fixation is unsuitable.
SN - 2250-0685
SN - 2321-3817
ER -